• Source: Kosaki overgrowth syndrome
  • Kosaki overgrowth syndrome is a rare syndrome caused by mutations in the PDGFRB gene.


    Presentation


    The features of this syndrome affect the face, skin, brain and the body.
    Face:

    downslanting palpebral fissures
    pointed chin
    prominent forehead
    proptosis
    thin upper lip
    wide nasal bridge
    Skin:

    fragile
    hyperelastic
    Brain:

    Low IQ
    Periventricular white matter lesions
    Body:
    The height, lower-segment, hand, and foot length are all greater than usual.


    Genetics


    No inheritance pattern has been described as these mutations appear to have arisen de novo. This syndrome is due to mutations in a single copy of the PDGFRB gene.


    Treatment




    History


    This condition was first described in Japan in 2011 by Watanabe et al. These authors thought the condition was the Shprintzen-Goldberg syndrome but the patient lacked a mutation in the SKI gene. A second case was described by Takenouchi et al in 2015. These authors recognised that this condition was novel and on performing a whole genome sequencing found mutations in the PDGFRB gene. A further 24 cases were reported in 2017 by Gawliński et al.


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    External links

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